neurological and vascular manifestations caused by ethe1 gene mutation: report of two cases of ethylmalonic encephalopathy abstract

نویسندگان

alireza tavasoli tehran university of medical science

parastoo rostami tehran university of medical science

mahmoud reza ashrafi tehran university of medical university

parvaneh karimzadeh shahid beheshti university of medical science

چکیده

abstract objective ethylmalonic encephalopathy (ee) is a severe mitochondrial disease of early infancy clinically characterized by a combination of developmental delay, progressive pyramidal signs and vascular lesions including petechial purpura, orthostatic acrocyanosis and chronic hemorrhagic diarrhoea. biochemical hallmarks of the disease are persistently high levels of lactate, and c4–c5-acylcarnitines in blood, markedly elevated urinary excretion of methylsuccinic and ethylmalonic (ema) acids. here we report two patients with ee that in one patient mutation analysis based on pcr amplification and sequencing of all coding exons and the exon-intron boundaries including of the ethe1 gene showed a homozygous mutation, c.c487t in exon 4.

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Neurological and Vascular Manifestations of Ethylmalonic Encephalopathy

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neurological and vascular manifestations of ethylmalonic encephalopathy

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عنوان ژورنال:
iranian journal of child neurology

جلد ۱۱، شماره ۲، صفحات ۰-۰

کلمات کلیدی
[ ' e t h y l m a l o n i c e n c e p h a l o p a t h y ' , ' s h o r t c h a i n a c y l c o a d e h y d r o g e n a s e ' , 2 , ' m e t h y l b r a n c h e d c h a i n a c y l c o a d e h y d r o g e n a s e ' ]

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